Alpha-1 anti-trypsin deficiency and Henoch-Schönlein purpura associated with anti-neutrophil cytoplasmic and anti-endothelial cell antibodies of immunoglobulin-A isotype.

TitleAlpha-1 anti-trypsin deficiency and Henoch-Schönlein purpura associated with anti-neutrophil cytoplasmic and anti-endothelial cell antibodies of immunoglobulin-A isotype.
Publication TypeJournal Article
Year of Publication2005
AuthorsPatterson CC, Ross P, Pope-Harman AL, Knight DA, Magro CM
JournalJ Cutan Pathol
Volume32
Issue4
Pagination300-6
Date Published2005 Apr
ISSN0303-6987
KeywordsAdult, alpha 1-Antitrypsin Deficiency, Antibodies, Antineutrophil Cytoplasmic, Antibodies, Antiphospholipid, Autoantibodies, Fatal Outcome, Fluorescent Antibody Technique, Direct, Humans, Immunoglobulin A, Immunoglobulin Isotypes, Liver, Lung, Male, Purpura, Schoenlein-Henoch
Abstract

Alpha-1 anti-trypsin (A1AT) deficiency is an inherited enzyme deficiency that manifests with fatal lung and liver complications. In addition to pulmonary and hepatic involvement, the disease has also been linked to an increased incidence of vasculitic syndromes and autoimmune diseases, including Wegener's granulomatosis, microscopic polyarteritis nodosa and Henoch-Schonlein purpura (HSP). HSP, a systemic, small-vessel vasculitis syndrome, is characterized by a non-thrombocytopaenic purpuric rash, arthralgia, abdominal pain and nephritis. Both A1AT deficiency and HSP have been associated with anti-neutrophil cytoplasmic antibodies (ANCA) and anti-endothelial cell antibodies (AECA). We report a case of a 40-year-old man with severe A1AT deficiency, who developed HSP associated with AECA, ANCA and anti-phospholipid antibodies of the immunoglobulin-A isotype.

DOI10.1111/j.0303-6987.2005.00304.x
Alternate JournalJ Cutan Pathol
PubMed ID15769280
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